Status:

COMPLETED

Safety and Efficacy of Albuterol in Individuals With Late-onset Pompe Disease

Lead Sponsor:

Duke University

Conditions:

Pompe Disease

Eligibility:

All Genders

18+ years

Phase:

PHASE1

PHASE2

Brief Summary

In this study the study team proposes to investigate the efficacy of albuterol on motor function of individuals with Late Onset Pompe Disease (LOPD) who are receiving enzyme replacement therapy, given...

Eligibility Criteria

Inclusion

  • Diagnosis of Pompe disease by blood acid alpha-glucosidase assay and acid alpha-glucosidase gene sequencing,
  • Age: 18+ years at enrollment.
  • Receiving enzyme replacement therapy at standard dose (20 mg/kg every 2 weeks) for at least 52 weeks.
  • Subjects are capable of giving written consent.

Exclusion

  • Continuous invasive ventilation (via tracheostomy or endotracheal tube).
  • Clinically relevant illness within two weeks of enrollment including fever \> 38.2 C, vomiting more than once in 24 hours, seizure, or other symptom deemed contraindicative to new therapy.
  • Chronic heart disease (Myocardial infarction in the past 2 months, arrhythmia, cardiomyopathy).
  • History of seizure disorder.
  • History of diabetes.
  • Hypokalemia.
  • History of hyperthyroidism.
  • Pregnancy.
  • Patients on a non-standard schedule for enzyme replacement therapy; for example, weekly infusions as opposed to infusions every two weeks.
  • Anti-rhGAA antibody titer \> 1:100,000
  • History of hypersensitivity to Beta 2-agonist drugs such as albuterol, levalbuterol (Xopenex), bitolterol (Tornalate), pirbuterol (Maxair), terbutaline, salmeterol (Serevent)..
  • The use of the following medications:
  • diuretics (water pill);
  • digoxin (digitalis, Lanoxin);
  • beta-blockers such as atenolol (Tenormin), metoprolol (Lopressor), and propranolol (Inderal);
  • tricyclic antidepressants such as amitriptyline (Elavil, Etrafon), doxepin (Sinequan), imipramine (Janimine, Tofranil), and nortriptyline (Pamelor);
  • Monoamine oxidase inhibitors such as isocarboxazid (Marplan), phenelzine (Nardil), rasagiline (Azilect), selegiline (Eldepryl, Emsam), or tranylcypromine (Parnate); or
  • bronchodilators such as albuterol, levalbuterol (Xopenex), bitolterol (Tornalate), pirbuterol (Maxair), terbutaline (Brethine, Bricanyl), salmeterol (Serevent), isoetharine (Bronkometer), metaproterenol (Alupent, Metaprel), or isoproterenol (Isuprel Mistometer) within 12 weeks prior to enrollment.

Key Trial Info

Start Date :

June 1 2013

Trial Type :

INTERVENTIONAL

Allocation :

ACTUAL

End Date :

December 16 2016

Estimated Enrollment :

16 Patients enrolled

Trial Details

Trial ID

NCT01885936

Start Date

June 1 2013

End Date

December 16 2016

Last Update

July 15 2019

Active Locations (1)

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Page 1 of 1 (1 locations)

1

Duke University Medical Center

Durham, North Carolina, United States, 27710