Status:

RECRUITING

Evaluation of A Clinical Diagnostic Test for CRDS

Lead Sponsor:

Population Health Research Institute

Collaborating Sponsors:

Canadian Institutes of Health Research (CIHR)

Conditions:

Calcium Release Deficiency Syndrome (CRDS)

Eligibility:

All Genders

Phase:

NA

Brief Summary

Calcium Release Deficiency Syndrome (CRDS) is a novel inherited arrhythmia syndrome secondary to RyR2 loss-of-function that confers a risk of sudden cardiac death. Diagnosis of CRDS presently requires...

Detailed Description

RyR2 loss-of-function variants have recently been established as causative for a new disease termed calcium release deficiency syndrome (CRDS) that confers a risk of malignant ventricular arrhythmias ...

Eligibility Criteria

Inclusion

  • Cohort 1: Calcium Release Deficiency Syndrome (CRDS) Cases
  • Inclusion criteria:
  • • Presence of an RyR2 variant confirmed to be loss-of-function on in vitro testing
  • Exclusion criteria:
  • • Unable to provide informed consent
  • Cohort 2: Catecholaminergic Polymorphic Ventricular Tachycardia (CPVT) Cases
  • Inclusion criteria:
  • Satisfy a clinical phenotype consistent with the Expert Consensus Statement
  • Presence of a confirmed or presumed pathogenic gain-of-function RyR2 variant OR homozygous or compound heterozygous for likely pathogenic/pathogenic CASQ2 variants
  • Exclusion criteria:
  • Unable to provide informed consent
  • Use of a QT prolonging medication, aside from flecainide, at the time of the burst pacing maneuvers
  • Cohort 3: Survivors of Unexplained Cardiac Arrest (UCA)
  • Inclusion criteria:
  • Cardiac arrest requiring cardioversion or defibrillation that remains unexplained following an ECG, echocardiogram, coronary assessment, cardiac MRI, and exercise treadmill test
  • Undergone genetic testing that includes screening of RyR2\*
  • Exclusion criteria:
  • Unable to provide informed consent
  • Use of a QT prolonging medication at the time of the burst pacing maneuvers
  • Among survivors of UCA that possess a rare RyR2 variant in the absence of a CPVT phenotype, in vitro functional testing will be performed in order to confirm it is not loss- or gain-of-function (and will be arranged through the laboratory of Dr. Wayne Chen at the University of Calgary).
  • Cohort 4: SVT controls
  • Inclusion criteria:
  • • Undergoing an invasive electrophysiology study
  • Exclusion criteria:
  • Ventricular cardiomyopathy
  • Ventricular pre-excitation
  • Long QT syndrome
  • Use of a QT prolonging medication at the time of the EP study
  • Use of a Class I or Class III anti-arrhythmic drug at the time of the EP study
  • Known obstructive coronary artery disease (existing coronary stenosis \>50%)
  • Unable to provide informed consent

Exclusion

    Key Trial Info

    Start Date :

    February 2 2023

    Trial Type :

    INTERVENTIONAL

    Allocation :

    ESTIMATED

    End Date :

    March 1 2026

    Estimated Enrollment :

    400 Patients enrolled

    Trial Details

    Trial ID

    NCT06188689

    Start Date

    February 2 2023

    End Date

    March 1 2026

    Last Update

    December 11 2025

    Active Locations (18)

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    Page 1 of 5 (18 locations)

    1

    University of California

    San Francisco, California, United States, 94143

    2

    Mayo Clinic

    Rochester, Minnesota, United States, 55905

    3

    University of Washington

    Seattle, Washington, United States, 98195

    4

    Antwerp University Hospital

    Edegem, Antwerp, Belgium, 2650